spondyloepiphyseal dysplasia

definition

·      heterogenous group of disorders

·      primary involvement of vertebrae and epiphyseal centres

·      resulting short-trunk dwarfism

Spondyloepiphyseal dysplasia congenita

definition

·      specific SED

epidemiology

·      transmitted as autosomal dominant

·      most cases sporadic (new mutation)

pathology

·      disorder of growth plate

·      abnormality of proliferative zone

·      microcystic areas

·      surrounded by ring of abnormal chondrocytes

clinical

·      short limbs

·      esp. proximal and middle segments

·      normal hands and legs

·      even shorter trunk

·      neck almost absent

·      cleft palate

·      pectus carinatum and barrel-shaped chest

·      increased lumbar lordosis

·      protruberant abdomen

·      hip flexion contractures

·      genu valgum

·      club foot

Radiology

·      epiphyses appear late

Spine

·      platyspondyly (flat or oval vertebral bodies)

·      odontoid hypoplasia

·      thoracic kyphoscoliosis

·      lumbar lordosis

Hip

·      delayed ossification of capital femoral epiphysis

·      coxa vara

·      varus may progress to discontinuity of femoral neck

·      may be progressive dislocation

medical complications

·      eye problems common

·      myopia

·      retinal detachment

Orthopaedic complications
Neck

·      odontoid hypoplasia leads to instability

·      may result in cervical myelopathy

·      treated with posterior atlantoaxial or occipitoaxial fusion

Spine

·      kyphoscoliosis usually progresses in adolescence

·      should be braced early

·      if fails, fusion indicated

Hip

·      if coxa vara severe, intertrochanteric osteotomy indicated

·      valgus and extension